EVIDENCE THAT ABNORMAL PLATELET FUNCTIONS IN HUMAN CHEDIAK-HIGASHI-SYNDROME ARE THE RESULT OF A LACK OF DENSE BODIES
- 1 January 1983
- journal article
- research article
- Vol. 111 (3) , 307-314
Abstract
The structure and functions of platelets from 3 patients with the Chediak-Higashi syndrome were examined. Electron-microscopic observations revealed a large reduction in the number of serotonin-storage granules or dense bodies but otherwise normal ultrastructure and normal amounts of .alpha.-granules and catalase-positive granules. The number of mepacrine-labeled granules was also reduced. Platelets contained normal amounts of .beta.-thromboglobulin and Platelet Factor 4. The platelet release reaction studied with thrombin as the inducer was impaired. The serotonin uptake by the patients'' platelets was low and not inhibited by reserpine, and its metabolism was increased. Apparently, platelets from human Chediak-Higashi syndrome are deficient in the storage pool of dense granule substances, and this granule defect evidently has an influence on the release mechanism of other granule constituents.This publication has 25 references indexed in Scilit:
- Initial characterization of human platelet mepacrine‐labelled granules isolated using a short metrizamide gradientBritish Journal of Haematology, 1982
- Mepacrine Stains the Dense Bodies of Human Platelets and not Platelet LysosomesBritish Journal of Haematology, 1981
- Characterization of platelets from normal mink and mink with the Chediak‐Higashi syndromeAmerican Journal of Hematology, 1979
- Giant platelet granules in a child with the chediak‐higashi syndromeAmerican Journal of Hematology, 1979
- A syndrome associating partial albinism and immunodeficiencyThe American Journal of Medicine, 1978
- Studies on a new variant of the Hermansky-Pudlak syndrome: Qualitative, ultrastructural, and functional abnormalities of the platelet-dense bodies associated with a phospholipase a defectAmerican Journal of Hematology, 1978
- Abnormal Platelet Function in Chediak‐Higashi SyndromeBritish Journal of Haematology, 1977
- Studies of Platelet 5-Hydroxytryptamine (Serotonin) in Storage Pool Disease and AlbinismJournal of Clinical Investigation, 1974
- The Platelet Defect Associated with AlbinismBritish Journal of Haematology, 1972
- Enzymatic Activities, ADP‐Induced Aggregation and Survival in Vivo as Criteria of Platelet Viability during StorageTransfusion, 1967