Abstract
A case history was reported of a 44 yr old man with a 6 yr history of psychomotor seizures. He described persistent olfactory hallucinations of an unpleasant nature which he believed were from himself. The symptoms conformed to the pattern observed in the olfactory reference syndrome, a recently described but apparently quite discrete psychiatric disorder. There were certain atypical features. At a later stage unilateral anosmia was noted. Radiological examination then demonstrated an arterio-venous malformation in the right frontal lobe. The relationship between the malformation and the psychomotor seizures, and the implications that each has for the development of an olfactory reference syndrome were discussed.