Variant maple syrup urine disease in mother and daughter.
- 18 August 1973
- journal article
- Vol. 109 (4) , 299-300 passim
Abstract
Intermittent MSUD in a mother and her daughter is reported. Fibroblast cultures were studied for branched-chain keto acid decarboxylase and results show that the mother has approximately 12% while the daughter has 5% of the normal enzyme activity. Other key members in the family were also studied for enzyme activity. It appears that the child has inherited an abnormal gene from her homozygous mother and another abnormal gene from her heterozygous father.A classification based on the degree of residual enzyme activity and protein tolerance places the mother in grade III and the daughter in grade II category. Classical MSUD, where the enzyme activity is less than 2% of normal, belongs to grade I.This publication has 9 references indexed in Scilit:
- BIOCHEMICAL STUDIES ON A VARIANT OF BRANCHED CHAIN KETOACIDURIA IN A 19-YEAR-OLD FEMALEPediatrics, 1971
- A VARIANT FORM OF BRANCHED‐CHAIN KETO ACIDURIAActa Paediatrica, 1971
- THIAMINE-RESPONSIVE MAPLE-SYRUP-URINE DISEASEThe Lancet, 1971
- A new variant of maple syrup urine disease (branched chain ketoaciduria): Clinical and biochemical evaluationThe American Journal of Medicine, 1970
- METHYLMALONIC ACIDEMIA AND VITAMIN B12 DEPENDENCYActa Paediatrica, 1970
- [LEUCINOSIS: A VARIANT OF BRANCHED-CHAIN KETO-ACIDURIA].1965
- Late Manifesting Variant of Branched-Chain Ketoaciduria (Maple Syrup Urine Disease)Acta Paediatrica, 1964
- Maple Syrup Urine DiseaseAmerican Journal of Diseases of Children, 1963
- Clinical and biochemical observations on an apparently nonfatal variant of branched-chain ketoaciduria (maple syrup urine disease).1961